Pentafid tongue: A new entity

ABSTRACT

Tongue plays a pivotal role in both physiological and functional life of human beings. Structural and developmental abnormalities of the tongue in various forms have been reported in isolation or in combination with various syndromes. Though cases of bifid tongues have been mentioned in literature, no reports of pentafid tongue have been reported till date. Here we describe a unique case of congenital pentafid tongue along with bilateral polydactyly and its surgical management.

KEY WORDS

Pentafid tongue - polydactyly - surgical technique - tongue shaping

• REFERENCES

• 1 Almeida LE, Ulbrich L, Togni F. Mandible cleft: Report of a case and review of the literature. J Oral Maxillofac Surg 2002; 60: 681-4
• 2 Emmanouil-Nikoloussi E, Kerameos-Foroglou C. Congenital syndromes connected with tongue malformations. Bull Assoc Anat (Nancy) 1992; 76: 67-72
• 3 Avery JK. Essentials of Oral Histology and Embryology: A Clinical Approach. 3rd ed. St. Louis: Mosby; 2000: p. 29-30
• 4 Stones HH. Oral and Dental Diseases. 4th ed. Edinburgh: Churchill Livingstone; 1962: p. 12
• 5 Mattei JF, Aymé S. Syndrome of polydactyly, cleft lip, lingual hamartomas, renal hypoplasia, hearing loss, and psychomotor retardation: Variant of the Mohr syndrome or a new syndrome?. J Med Genet 1983; 20: 433-5
• 6 Kulkarni U, Kulkarni DU. Bifid tongue - A case report. NJCA 2013; 2: 97-8
• 7 Martinot VL, Manouvrier S, Anastassov Y, Ribiere J, Pellerin PN. Orodigitofacial syndromes type I and II: Clinical and surgical studies. Cleft Palate Craniofac J 1994; 31: 401-8
• 8 Wey PD, Neidich JA, Hoffmann LA, LaTrenta GS. Midline defects of the orofaciodigital syndrome type VI (Váradi syndrome). Cleft Palate Craniofac J 1994; 31: 397-400
• 9 Rao S, Oak S, Wagh M, Kulkarni B. Congenital midline palatomandibular bony fusion with a mandibular cleft and a bifid tongue. Br J Plast Surg 1997; 50: 139-41
• 10 James AW, Culver K, Hall B, Golabi M. Bifid tongue: A rare feature associated with infants of diabetic mother syndrome. Am J Med Genet 2007; 143A: 2035-9